|Year : 2017 | Volume
| Issue : 4 | Page : 346-348
Localized hypertrichosis at unusual sites
Anshul Maheshwari, Daulat Ram Dhaked, Ram Singh Meena
Department of Dermatology, Venereology and Leprology, SMS Medical College, Jaipur, Rajasthan, India
|Date of Web Publication||29-Sep-2017|
Ram Singh Meena
Department of Dermatology, Venereology and Leprology, SMS Medical College, Jaipur, Rajasthan
Source of Support: None, Conflict of Interest: None
Localized hypertrichosis is a rare entity characterized by circumscribed patches of terminal hair. It may be associated with many underlying systemic abnormalities. In our case, a 5-year-old girl presented with complaints of multiple patches of hypertrichosis without any systemic abnormality since the last 4 years. We are reporting this case due to the rarity of hypertrichosis at abnormal sites.
Keywords: Hypertrichosis cubiti, hypertrichosis, localized hypertrichosis
|How to cite this article:|
Maheshwari A, Dhaked DR, Meena RS. Localized hypertrichosis at unusual sites. Indian J Paediatr Dermatol 2017;18:346-8
| Introduction|| |
Hypertrichosis is described as growth of an excessive amount of hair on any area of the body and above the normal for the age, sex, and race of an individual. It can be classified into generalized and localized type. We report a 5-year-old girl with multiple patches of localized hypertrichosis without any pigmentary and systemic abnormality.
| Case Report|| |
A 5-year-old girl came to us with multiple patches of localized hair over body. Dermatology consultation was taken due to cosmetic reasons. There was no hair growth at birth, but after a period of 6 months, a patch of hair first developed over back of the right thigh [Figure 1]. Steadily, the hairs increased in size to about 2–3 cm in duration of 2 years. Similarly, hair also developed over the body symmetrically over the arms, face, and on the hip region.
Dermatological examination revealed multiple ill-defined patches of hair over the right thigh and bilaterally symmetrical over the elbows, hip, and face [Figure 2], [Figure 3], [Figure 4]. The hairs were terminal, pigmented of size variable from 2 cm over the face to about 4 cm over the thigh and elbows. The skin over the patch was normal without any pigment abnormality.
On investigating the patient, thyroid-stimulating hormone, cortisol, hormonal profile, routine counts, and ultrasonography abdomen came out to be normal.
As the patient had cosmetic concern predominantly, we counseled the patient to use mechanical removal of hair by scissors and using chemical anti-epilatory creams and advised the patient to go for laser removal after puberty.
| Discussion|| |
Primary hypertrichosis has been defined based on the age of onset as congenital or acquired and on the extent of distribution as localized or generalized. Localized hypertrichosis is a rare entity characterized by the presence of hair in an asymmetrical or bilaterally symmetrical similar fashion. Localized hypertrichosis may be found as an isolated clinical lesion or in association with congenital melanocytic nevi, congenital Becker nevi, nevoid hypertrichosis, nevus pilosus, smooth muscle hamartomas, plexiform neurofibromas, and linear epidermal nevi.,, It may present with an underlying spina bifida occulta, diastematomyelia, or kyphoscoliosis.
There are multiple case reports, of which occurring at special anatomic sites such as hypertrichosis cubiti, hairy palms and soles, hairy pinna, anterior and posterior cervical hypertrichosis, and hypertrichosis of nasal tip. In most of the cases, hypertrichosis is of idiopathic type but in some cases, autosomal dominant and recessive forms had also been reported.,
In this patient, hypertrichosis was not present in any of these patterns. The patient had hypertrichosis cubiti with hypertrichosis involving bilaterally symmetrical over face, hip and asymmetrically over right thigh. Due to rarity of this presentation, we are reporting this case.
Treatment generally involves various measures such as bleaching, trimming, waxing, physical and chemical depilatories, electrolysis, intense pulsed light therapy, and laser hair removal.
Declaration of Patient Consent
The authors certify that they have obtained all appropriate patient consent forms. In the form the patient(s) has/have given his/her/their consent for his/her/their images and other clinical information to be reported in the journal. The patients understand that their names and initials will not be published and due efforts will be made to conceal their identity, but anonymity cannot be guaranteed.
Financial support and sponsorship
Conflicts of interest
There are no conflicts of interest.
| References|| |
Vergani R, Betti R, Martino P, Crosti C. Giant nevoid hypertrichosis in an Iranian girl. Pediatr Dermatol 2002;19:64-6.
Schaffer JV, Chang MW, Kovich OI, Kamino H, Orlow SJ. Pigmented plexiform neurofibroma: Distinction from a large congenital melanocytic nevus. J Am Acad Dermatol 2007;56:862-8.
Leung AK. Giant congenital nevomelanocytic nevus. Can J CME 2006;18:68.
Leung AK, Fong JH. Non-hairy Becker's nevus. Can J Diagn 2004;21:47.
Izci Y, Gonul M, Gonul E. The diagnostic value of skin lesions in split cord malformations. J Clin Neurosci 2007;14:860-3.
Braddock SR, Jones KL, Bird LM, Villegas I, Jones MC. Anterior cervical hypertrichosis: A dominantly inherited isolated defect. Am J Med Genet 1995;55:498-9.
Reed OM, Mellette JR Jr, Fitzpatrick JE. Familial cervical hypertrichosis with underlying kyphoscoliosis. J Am Acad Dermatol 1989;20:1069-72.
[Figure 1], [Figure 2], [Figure 3], [Figure 4]